IMMUNOGENIC CONSTRUCT COMPRISING AN EBV-CELL ANTIGEN AND A TARGETING MOIETY AND APPLICATIONS THEREOF

20180360950 · 2018-12-20

Assignee

Inventors

Cpc classification

International classification

Abstract

The present invention generally relates to an immunogenic construct,useful for redirecting an EBV-existing immune response towards an undesired target cell and/or microorganism, to methods for preparing said conjugate, to a pharmaceutical applications comprising said conjugate, and to medical applications thereof.

Claims

1. An immunogenic conjugate comprising: i) a moiety binding to a target cell and/or microorganism; and ii) an Epstein-Barr Virus (EBV) B-cell antigen.

2. The immunogenic conjugate according to claim 1, wherein said target-binding moiety is covalently coupled to said Epstein-Barr Virus B-cell antigen.

3. The immunogenic conjugate according to claim 1 or 2, wherein said moiety is a ligand-binding protein selected from the group consisting of antibodies, binding fragments thereof, antibody mimetics, cell-surface receptors, cell-surface ligands and any combination thereof.

4. The immunogenic conjugate according to claim 3, wherein said antibody fragments are selected from the group consisting of Fab antibodies, Fab antibodies, F(ab)2 antibodies, Fv antibodies, single chain antibodies (scFv), and single-domain antibodies, and any combination thereof.

5. The immunogenic conjugate according to claim 1 or 2, wherein said moiety is a non-proteic moiety selected from the group consisting of vitamins, carbohydrates, glycosaminoglycans, small nucleic acids, small chemical compounds, and any combination thereof.

6. The immunogenic conjugate according to any one of claims 1 to 5, wherein said Epstein-Barr Virus B-cell antigen is selected from the group consisting of the P18 antigens of sequence SEQ ID NO: 15, the P23 antigens of sequence SEQ ID NO: 16, functional variants and functional fragments thereof, and any combination thereof.

7. The immunogenic conjugate according to claim 6, with the proviso that, when said moiety comprises a thiol group, the functional variants and functional fragments of the P18 and/or P23 antigens do not comprise any cysteine residue.

8. The immunogenic conjugate according to claim 7, wherein said functional variants are selected from the group consisting of the P18 antigen functional variants of sequence SEQ ID NO: 39 and the P23 antigen functional variants of sequence SEQ ID NO: 40.

9. The immunogenic conjugate according to claim 6 or 7, wherein said functional fragments comprise between about 10 amino acid residues and about 150 amino acid residues of said antigens.

10. The immunogenic conjugate according to claim 9, wherein said functional fragments are P18 antigen functional fragments comprising at least the sequence selected from the group consisting of SEQ ID NO:75 and SEQ ID NO: 43 to SEQ ID NO: 49, and/or P19 antigen functional fragments comprising at least the sequence selected from the group consisting of SEQ ID NO: 50 and SEQ ID NO: 51.

11. The immunogenic conjugate according to claim 10, wherein said P18 antigen functional fragments comprise or consist of the sequence selected from the group consisting of SEQ ID NO:76 and SEQ ID NO: 52 to SEQ ID NO: 58, and/or said P23 antigen functional fragments comprise or consist of the sequence selected from the group consisting of SEQ ID NO: 59 and SEQ ID NO: 60.

12. The immunogenic conjugate according to any one of claims 1 to 11, wherein the target cell is a diseased cell, preferably a cancer cell or a cell infected by a pathogen such as a virus, a bacterium, a fungus and/or a parasite, and/or the target microorganism is a pathogenic microorganism, preferably a virus, a bacterium, a fungus, and/or a parasite.

13. The immunogenic conjugate according to claim 12, wherein: said diseased cell is a malaria infected erythrocyte and/or said pathogenic microorganism is Plasmodium falciparum; or said diseased cell is a cancer cell.

14. A pharmaceutical composition comprising at least one immunogenic conjugate as defined in any one of claims 1 to 13 and at least one pharmaceutically acceptable excipient.

15. The immunogenic conjugate as defined in any one of claims 1 to 13, or the pharmaceutical composition as defined in claim 14, for use as a medicament.

Description

BRIEF DESCRIPTION OF THE DRAWINGS

[0230] FIG. 1. IMAC purification of the conjugates DARC.sub.VHH-EBV P18 antigen and DARC.sub.VHH-EBV P23 antigen. Ni-NTA purification of DARC.sub.VHH-P23 under native (A-B) or of DARC.sub.VHH-P18 and DARC.sub.VHH-P23 under denaturing conditions (C-D). Following SDS PAGE, protein gels were stained with Coomassie blue (A and C) or transferred onto a nitrocellulose membrane for western blot analysis using an anti-His as probing antibody (B and D).

[0231] FIG. 2. IMAC purification of the conjugates DARC.sub.VHH-EBV mutated P18 antigen and DARC.sub.VHH-EBV mutated P23 antigen. Ni-NTA purification of the mutated conjugates DARC.sub.VHH-P18 (C56S)* and DARC.sub.VHH-P23 (C46S)* under native conditions. Following SDS PAGE, protein gels were stained with Coomassie blue.

[0232] FIG. 3. Gel filtration chromatography of the conjugates DARC.sub.VHH-EBV mutated P18 antigen and DARC.sub.VHH-EBV P18 antigen fragments as well as of the anti-DARC VHH alone. Following IMAC purification, DARC.sub.VHH-P18 (056S)* (A), DARC.sub.VHH-P18F2 (B), DARC.sub.VHH-P18F3 (C), DARC.sub.VHH-P18F4 (D), and DARC.sub.VHH (E) were subjected to size exclusion chromatography.

[0233] FIG. 4. IMAC purification and gel filtration chromatography purification of the conjugates DARC.sub.VHH-EBV P18 and VAR2CSA.sub.VHH-EBV P18 (mutated and fragments). Following IMAC purification, DARC.sub.VHH-P18(C56S)* was subjected to size exclusion chromatography (A). Coomassie blue staining of purified conjugates DARC.sub.VHH-P18 fragments and VAR2CSA.sub.VHH-P18F2 fragments as well as of their purified respective molecular targets DARC and VAR2CSA (B). The recombinant DARC.sub.325 protein contains the epitope targeted by DARC.sub.VHH, whereas the recombinant DARC.sub.403 lacks the epitope sequence. The full-length extracellular part of VAR2CSA comprises the 6 DBL domains (DBL1-DBL6), VAR2CSA.sub.VHH targeting the DBL4 domain.

[0234] FIG. 5. Comparative analysis of the affinity of non-conjugated versus conjugated DARC.sub.VHH and VAR2CSA.sub.VHH for their respective molecular targets, i.e. DARC and VAR2CSA. Full-length recombinant DARC.sub.325 and VAR2CSA (3D7-DBL1X-6) were immobilized on CM5 chips and analytes were injected at different concentrations. The affinity constants of DARC.sub.VHH-P18F2, DARC.sub.VHH-P18F3, DARC.sub.VHH-P18F4, DARC.sub.VHH for DARC.sub.325 and of VAR2CSA.sub.VHH-P18F2, VAR2CSA.sub.VHH-P18F3, VAR2CSA.sub.VHH for VAR2CSA were not significantly modified by the EBV-antigen conjugations.

[0235] FIG. 6. Immune recognition of the DARC.sub.VHH-EBV P18 and VAR2CSA.sub.VHH-EBV P18 conjugates (fragments). Example of antibody titer (IgG) determination towards DARC.sub.VHH-EBV P18F2. The antibody titer for donor 20120617 was regarded as the plasma dilution at which 50% of the maximum OD signal was reached (A). Comparative immune recognition (IgG) by 22 different plasma samples of DARC.sub.VHH-P18F2, DARC.sub.VHH-P18F3, DARC.sub.VHH-P18F4, DARC.sub.VHH, VAR2CSA.sub.VHH-P18F2, VAR2CSA.sub.VHH-P18F3, VAR2CSA.sub.VHH and of MBP EBV-P18 and MBP P23 (B). BSA and MBP were used as controls.

[0236] FIG. 7. Binding of the conjugate DARC.sub.VHH-EBV P18 antigen fragment F2 to its native target, i.e. DARC expressed at the erythrocyte surface of a DARC+ donor. DARC+ erythrocytes were incubated with serial dilutions of DARC.sub.VHH-P18F2. Membrane bound protein was monitored by flow cytometry using an anti-His PE-conjugated antibody.

[0237] FIG. 8. Erythrocytes opsonization mediated by DARC.sub.VHH-EBV P18 conjugates (mutated and fragments). (A) In order to demonstrate erythrocytes opsonization, DARC+ erythrocytes were incubated with DARC.sub.VHH-P18 (C56S)*, and subsequently with serial dilutions of human plasma (left panel). Membrane associated IgG were detected by flow cytometry using an anti-hlgG PE-conjugated antibody (right panel). A shift in fluorescence intensity (PE) reflects the presence of an immune complex at the erythrocyte cell surface (right panel) (B). Erythrocytes agglutination mediated by the conjugate DARC.sub.VHH-EBV P18 antigen fragment F3. DARC+ erythrocytes were incubated with DARC.sub.VHH-P18F3 and subsequently with serial dilutions of human plasma. Following centrifugation of the plate, erythrocytes from control conditions (without human plasma) formed a well-defined cell pellet (a,b,c) whereas erythrocytes incubated in presence of DARC.sub.VHH-P18F3 and human plasma formed diffused agglutinates (d, e, f) (B).

[0238] FIG. 9. Opsonic phagocytosis mediated by DARC.sub.VHH-EBV P18 conjugates (mutated and fragments). (A) In order to demonstrate that erythrocytes opsonization leads to phagocytosis, THP1 derived macrophages were incubated with CFSE-stained DARC.sup.+ erythrocytes pre-opsonized with DARC.sub.VHH-P18(C56S)*, and human IgG. After 3 hours, THP1 cells were analysed by flow cytometry. CFSE positive THP1 cells were regarded as cells having phagocyted at least one erythrocyte. (B) THP1 cells were incubated with CFSE-stained DARC.sup.+ erythrocytes pre-opsonized with DARC.sub.VHH-P18F3 and human IgG. After 3 hours, THP1 cells were analysed by flow cytometry. CFSE positive THP1 cells were regarded as cells having phagocyted at least one erythrocyte. (C) Opsonic phagocytosis mediated by DARC.sub.VHH-EBV P18 conjugates. In order to demonstrate that treatment of DARC+ erythrocytes with different DARC.sub.VHH-EBV P18 conjugates mediates cell opsonization and subsequent phagocytosis by THP1 cells, CFSE-stained erythrocytes were incubated with equimolar concentrations (10 nM) of DARC.sub.VHH, DARC.sub.VHH-EBV P18F2, DARC.sub.VHH-EBV P18F3, DARC.sub.VHH-EBV P18F4 and with 10% human plasma. Human plasma samples were screened for their reactivity to P18 and pooled according to their capability to recognize the EBV antigens in 3 groups: highly reactive to P18 (High), moderately reactive to P18 (Medium) or low reactive (Low). After 3 h co-incubation, THP1 cells were analysed by flow cytometry. CFSE positive THP1 cells were regarded as cells having phagocyted at least one erythrocyte. Results are expressed as fold increase compared to the experimental condition without any conjugate, red blood cells (RBC) only.

[0239] FIG. 10. IMAC purification and gel filtration chromatography purification of the hCD20.sub.ScFv-P18F3 and VAR2CSA-P18F3 conjugates. Following IMAC purification, hCD20.sub.ScFv-P18F3 and VAR2CSA-P18F3 were subjected to size exclusion chromatography. Coomassie blue staining of hCD20.sub.ScFv-P18F3, VAR2CSA-P18F3 and of the naked proteins hCD20.sub.ScFv and VAR2CSA.

[0240] FIG. 11. Binding of the hCD20.sub.ScFv-P18F3 and VAR2CSA-P18F3 conjugates to their native target, i.e CD20 expressed at the surface of B cells and CSA expressed at the surface of cancer cells, respectively. CD20- and CSA-expressing RAJI cells were incubated with 50 g/ml of hCD20.sub.ScFv, hCD20.sub.ScFv-P18F3 or 50 g/ml of VAR2CSA, VAR2CSA-P18F3. Membrane bound protein was monitored by flow cytometry using a mouse anti-His antibody and an anti-mouse IgG-PE-conjugated antibody.

[0241] FIG. 12. CD20.sup.+ RAJI cells opsonization mediated by the hCD20.sub.ScFv-P18F3 conjugate. In order to demonstrate B cells opsonization, CD20.sup.+ RAJI cells were incubated with serial dilutions of hCD20.sub.ScFv or hCD20.sub.ScFv-P18F3 and subsequently with a constant human plasma dilution (1:100). (A) Membrane associated IgG were detected by flow cytometry using an anti-hlgG PE-conjugated antibody. A shift in fluorescence intensity (PE) reflects the presence of an immune complex at the cell surface. (B) Chart representation of the data generated by flow cytometry analysis.

[0242] FIG. 13. CSA.sup.+ RAJI cells opsonization mediated by the VAR2CSA-P18F3 conjugate. In order to demonstrate B cells opsonization, CSA.sup.+ RAJI cells were incubated with serial dilutions of VAR2CSA or VAR2CSA-P18F3 and subsequently with a constant human plasma dilution (1:100). (A) Membrane associated IgG were detected by flow cytometry using an anti-hlgG PE-conjugated antibody. A shift in fluorescence intensity (PE) reflects the presence of an immune complex at the cell surface. (B) Chart representation of the data generated by flow cytometry analysis.

[0243] FIG. 14. Complement activation mediated by hCD20.sub.ScFv-P18F3. In order to demonstrate that B cell opsonization mediated by hCD20.sub.ScFv-P18F3 is able to activate the complement cascade to the formation of the membrane-attack complex, CD20.sup.+ RAJI cells were incubated with 5 g/ml of hCD20.sub.ScFv or hCD20.sub.ScFv-P18F3 and subsequently with 10% EBV.sup.+ human plasma in its active form or heat inactivated. The deposition of the membrane-attack complex constitutive element C5-b9 was detected at the cell membrane surface after 1 h incubation using a mouse monoclonal anti-C5-b9 antibody and an anti-mouseIgG-PE-conjugated antibody. The slight C5-b9 deposition at the RAJI cell surface observed with active human plasma alone is most likely due to the activation of the alternative (antibody independent) pathway of the complement by the cancer cell line.

[0244] FIG. 15. Antibody Dependent Cell Cytotoxicity (ADCC) mediated by hCD20.sub.ScFv-P18F3 (A) and VAR2CSA-P18F3 (B). Activation of gene transcription through the NFAT pathway in the effector cells reflects the conjugates biological activity in ADCC and is quantified through the luciferase produced (luminescence readout). RAJI cells were incubated with saturating concentration of conjugates and subsequently with serial dilution of EBV.sup.+ human plasma. After a 6 h co-incubation with competent effector cells, NFAT pathway activation was monitored by reading the luminescence of each plate well (expressed in CPS: counts per seconds).

[0245] FIG. 16. IMAC purification and gel filtration chromatography purification of the conjugate EPCR-P18F3. Following IMAC purification, EPCR-P18F3 was subjected to size exclusion chromatography. (A) Coomassie blue staining of EPCR-P18F3 and (B) western blot analysis using an anti-His antibody. Gel filtration (GF) fractions containing purified EPCR-P18F3 were pooled and used in functional assays.

[0246] FIG. 17. Binding of the conjugate EPCR-P18F3 to its native target, i.e VAR19 expressed at the surface of Pf. infected erythrocytes. VAR19-expressing infected erythrocytes (iRBC) were incubated with serial dilutions of EPCR-P18F3 (ranging from 100 g/ml to 0.19 g/ml). Membrane bound protein was monitored by flow cytometry using a mouse anti-His antibody and an anti-mouse IgG-PE-conjugated antibody. (A) Morphological gating of cells. (B) TOPRO3 staining allowing the discrimination between infected red blood cells (iRBC) and non-infected red blood cells (RBC). Detection of membrane bound EPCR-P18F3 in (C) the iRBC population and (D) in the RBC population.

[0247] FIG. 18. Opsonic phagocytosis mediated by EPCR-P18F3. In order to demonstrate that VAR19-expressing infected erythrocytes (iRBC) opsonization mediated by EPCRP18F3 induces phagocytosis, THP1 derived macrophages were incubated with CFSE-stained VAR19-expressing iRBC pre-opsonized with EPCR-P18F3 and hlgG. After 3 hours, THP1 cells were analysed by flow cytometry. CFSE positive THP1 cells were regarded as cells having phagocyted at least one iRBC.

EXAMPLES

1. Material and Methods

[0248] 1.1. Construction of the Immunogenic Conjugates According to the Invention

[0249] The DNA sequences of BFRF3 and BLRF2 encoding for the EBV (B95-8 strain) P18 and P23 proteins were codon-optimized (Integrated DNA Technology) to maximize their expression in E. coli. Full length P18 and P23 recoded nucleotide sequences as well as truncated fragments thereof were cloned into the pET28a plasmid (Novagen) in order to express C-terminal His-tagged proteins, for purification purpose.

[0250] In some conjugates, a flexible linker of 20 amino-acids (GGGGS).sub.4 (SEQ ID NO: 7) has been added between the binding moiety (VHH, scFv, cell surface receptor, or cell-surface ligand) and the EBV-B cell P18 or P23 antigen in order to maintain, and if possible enhance, the proper functional attributes of the 2 different modules (i.e. of the moiety binding to the target cell and/or microorganism and of the EBV-B cell antigen) (Hu et al., 2004; Chen et al., 2013). The binding moiety sequences (except EPCR) were then inserted between the NcoI and NheI restriction sites of the modified pET28a plasmid. For the EPCR conjugate, the gene encoding soluble EPCR (residues S18-S210;[Uniprot:Q9UNN8; SEQ ID NO:14) was amplified by PCR from a human lung endothelium cDNA library and fused to a recoded gene fragment encoded for P18F3. The EPCR-P18F3 sequence was cloned into a pTT3 vector with a hexa-His C-terminal tag.

[0251] In the present study, the following conjugates were thus designed: [0252] EBV P18 full length antigen fused in frame to DARC.sub.VHH, with linker; [0253] EBV P23 full length antigen fused in frame to DARC.sub.VHH, with linker; [0254] EBV P18 mutated antigen fused in frame to DARC.sub.VHH, with and without linker; [0255] EBV P23 mutated antigen fused in frame to DARC.sub.VHH, with and without linker; [0256] various EBV P18 fragments fused in frame to DARC.sub.VHH, VAR2CSA.sub.VHH, VAR2CSA, hCD20scFv or EPCR, without linker; and [0257] various EBV P23 fragments fused in frame to DARC.sub.VHH, without linker.

[0258] These linkers can be summarized in the following Table 1.

TABLE-US-00015 TABLE1 Immunogenicconjugates targeting entire moeity EBVantigen corresponding (inN-terminal) linker (inC-terminal) sequence DARG.sub.VHH (GGGGS)4 P18(SEQIDNO:17) SEQIDNO:61 (SEQIDNO:9) (SEQIDNO:7) Smolareket (GGGGS)4 P18-C565(SEQIDNO:41) SEQIDNO:62 al.,2010 (SEQIDNO:7) none P18-C565(SEQIDNO:41) SEQIDNO:63 none P18F2(SEQIDNO:58) SEQIDNO:64 none P18F3(SEQIDNO:76) SEQIDNO:77 none P18F4(SEQIDNO:52) SEQIDNO:66 VAR2CSA.sub.VHH none P18F2(SEQIDNO:58) SEQIDNO:67 (SEQIDNO:11) none P18F3(SEQIDNO:76) SEQIDNO:78 Nunesetal., none P18F4(SEQIDNO:52) SEQIDNO:69 2014 DARC.sub.VHH (GGGGS)4 P23(SEQIDNO:23) SEQIDNO:70 (SEQIDNO:9) (SEQIDNO:7) Smolareket (GGGGS)4 P23-C465(SEQIDNO:42) SEQIDNO:71 al.,2010 (SEQIDNO:7) none P23-C465(SEQIDNO:42) SEQIDNO:72 none P23F2(SEQIDNO:60) SEQIDNO:73 none P23F3(SEQIDNO:59) SEQIDNO:74 CD20scFv none P18F3(SEQIDNO:76) SEQIDNO:81 Otzetal.,2009; Liuetal.,1987 (SEQIDNO:80) VAR2CSA none P18F3(SEQIDNO:76) SEQIDNO:83 (SEQIDNO:82) EPCR none P18F3(SEQIDNO:76) SEQIDNO:79 (SEQIDNO:14)

[0259] 1.2. Expression and Purification of the Conjugates

[0260] For protein expression, SHuffle E. coli (New England Biolabs) allowing cytoplasmic disulphide bonds formation were transformed with the different pET28a-based conjugates. Bacteria cultures were induced with 0.2 mM IPTG at OD.sub.600nm 0.5 and protein expression was carried out at 20 C. for 16 h. For protein purification, bacteria suspensions were thawed on ice and lysis was achieved by passing the cell suspensions through an EmulsiFlex-C5 high-pressure homogenizer. Soluble proteins were subjected to a 2 step purification process. His-tagged proteins were first purified on Ni-NTA Superflow (Qiagen) then passed through a Superdex 200 10/300 GL gel filtration column (GE Healthcare).

[0261] In particular, for the EPCR conjugate, FreeStyle 293-F cells (Invitrogen) were grown in Freestyle 293 serum free expression medium and transfected with the pTT3 vector containing the EPCR-P18F3 sequence following Invitrogen's recommendations. 72 hours post-transfection, cells were centrifuged and the culture medium was harvested. After filtration on a 0.22 m filter, supernatants were concentrated five times using a 10 kDa cut-off Vivaflow 200 System (Vivasciences). Soluble proteins were subjected to a 2 step purification process. His-tagged proteins were first purified on Ni-NTA Superflow (Qiagen) then passed through a Superdex 200 10/300 GL gel filtration column (GE Healthcare).

[0262] 1.3. Affinity Determination by Surface Plasmon Resonance

[0263] Interactions between the conjugates and their respective molecular targets were studied by surface plasmon resonance (SPR), using a Biacore X100 instrument (GE Healthcare). All experiments were performed in HBSEP buffer (GE Healthcare) at 25 uC. Recombinant full-length DARC.sub.325 or VAR2CSA protein was immobilized on the analysis Fc2 channel of a CM5 chip (GE Healthcare) by amine coupling to a total loading of 800 RU. Reference channel Fc1 was blocked with 1 M ethanolamine-HCl pH 8.5 using the same chemistry. Conjugates were injected at 30 L/min in dilution series over the coated chips. The highest concentration of conjugates was 1 mM and ten twofold serial dilutions were also injected. Between the injections, the chip surface was regenerated with 2 injections of 15 ml of 10 mM HCl pH2. The specific binding response was obtained by subtracting the response given by the analytes on Fc2 by the response on Fc1. The kinetic sensorgrams were fitted to a global 1:1 interaction Langmuir model using the manufacturer's software.

[0264] 1.4. Immune Recognition of the Conjugates

[0265] ELISA plates (Nunc) were coated with 100 ml per well of conjugates diluted in PBS at 1 g/ml and incubated at 4 C. overnight. BSA (2% in PBS) was coated for background measurement. After coating, the wells were blocked with PBS 2% BSA at room temperatureT for 1 h. After removing the blocking solution, human plasma dilutions in PBS 2% BSA were added and the plates were incubated at room temperature for 1 h. The wells were then washed 3 times with 150 ml of PBS 0.05% Tween20 (PBST). Human IgG binding was detected with a horseradish peroxidase-conjugated (HRP) anti-human IgG (Jackson Immunoresearch 709-036-098), diluted 1:4000 in PBS 2% BSA, incubated at room temperature for 1 h. After washing with PBST, the plates were developed with 100 ml per well of TMB (3,39,5,59-tetramethylbenzidine) substrate (Biorad) and absorbance was measured at 655 nm.

[0266] 1.5. Cell Surface Recognition by the Conjugates

[0267] The capacity of the DARC.sub.VHH-EBV conjugates to recognize the native DARC expressed at the surface of erythrocytes, the one of the hCD20.sub.ScFv-P18F3 conjugate to recognize the native CD20 protein expressed at the surface of B cells, the one of the VAR2CSA-P18F3 conjugate to recognize the native glycosaminoglycan chondroitin sulfate A (CSA) expressed at the surface of cancer cells, and the one of the EPCR-P18F3 conjugate to recognize the native VAR19 protein expressed at the surface of Plasmodium falciparum-infected cells, were tested by flow cytometry.

[0268] To do so, DARC+ erythrocytes (for DARC.sub.VHH-EBV conjugates), CD20.sup.+ RAJI cells (for the hCD20.sub.ScFv-P18F3 conjugate), CSA.sup.+ RAJI cells (for the VAR2CSA-P18F3 conjugate) or VAR19-expressing erythrocytes (for the EPCR-P18F3 conjugate) were incubated with serial dilution of conjugate in PBS 2% BSA, for 1 h at room temperature. The cells were then washed twice with PBS 2% BSA and incubated for 30 min at room temperature with a mouse anti-PentaHis IgG (Qiagen, Cat.no.34660) at 5 mg/ml diluted in PBS 2% BSA. After 30 min, cells were washed twice with PBS 2% BSA and incubated for 30 min at room temperature with a PE-conjugated goat F(ab)2 anti-mouse IgG (Beckman Coulter, IM0855, diluted 1:100 in PBS 2% BSA). Cells were washed with PBS and subjected to flow cytometry analysis. Data was acquired using a BD FACScanto II flow cytometer (Becton-Dickinson, San Jose, Calif.) and analysis was performed using the FLOWJO 8.1 software (Tree Star Inc.). Cellular debris were excluded from the analysis by appropriated gating using the forward and side scatters.

[0269] The reactivity of the tested conjugates to surface-expressed DARC (for DARC.sub.VHH-EBV conjugates), to surface of RAJI cells (for the hCD20.sub.ScFv-P18F3 and VAR2CSA-P18F3 conjugates), or to surface-expressed VAR19 (for the EPCR-P18 conjugate) was reflected by an increase geometric mean in fluorescence intensity in the PE channel (Geometric Mean PE).

[0270] 1.6. Opsonization Assays

[0271] For opsonization assays, DARC+ erythrocytes were incubated with a constant concentration of the DARC.sub.VHH-EBV conjugates in PBS 2% BSA, for 1 h at room temperature. The cells were then washed twice with PBS 2% BSA and incubated for 1 h at room temperature with serial dilutions of human plasma in PBS 2% BSA. Cells were then washed twice with PBS 2% BSA and incubated for 30 min at room temperature with a PE-conjugated donkey F(ab)2 anti-human IgG (Jackson Immunoresearch 709-116-098, diluted 1:100 in PBS 2% BSA). Cells were washed with PBS and subjected to flow cytometry analysis.

[0272] By contrast, RAJI cells were incubated with serial dilutions of the hCD20.sub.ScFv-P18F3 or VAR2CSA-P18F3 conjugate in PBS 2% BSA, for 1 h at room temperature. These cells were then washed twice with PBS 2% BSA and incubated for 1 h at room temperature with a constant human plasma dilution (1:100) in PBS 2% BSA. Said cells were then washed according to the same protocol as the one applied for DARC+ erythrocytes.

[0273] 1.7. Opsonic Phagocytosis Assays

[0274] The non-adherent human monocyte cell line THP-1 (Sigma) was maintained in 150 cm.sup.2 flasks with RPMI 1640 medium supplemented with 10% (v/v) fetal bovine serum (Gibco, Grand Island, N.Y.), 2 mM L-Glutamine, 100 units/ml penicillin and 100 ug/ml streptomycin (THP-1 culture medium). The cells were subcultured every 3 days and density was maintained at less than 210.sup.5 cells per ml; cultures were kept in a humidified 37 C. incubator with 5% (v/v) CO.sub.2 and 95% (v/v) air.

[0275] THP-1 cells were seeded at 2.510.sup.5 cells per well in 6-well plates and the volume of each well was made to 3 ml with THP-1 culture media. To obtain macrophages, the cells were differentiated using 10 ng/ml phorbol 12-myristate 13-acetate for 24 h in 5% (v/v) CO.sub.2 at 37 C. The supernatant and unattached cells were removed by aspiration and adherent macrophages were washed twice with THP-1 culture medium before the wells were filled with 3 ml of fresh THP-1 culture medium. These were further incubated for 48 h before performing phagocytic assay.

[0276] Erythrocytes were labeled with CellTraceCFSE according to the manufacturer's instructions and opsonized with the conjugates and human plasma as described above. Labeled and opsonized erythrocytes were co-inbubated with THP-1 derived macrophages for 3 h. Erythrocytes were washed out from the wells and macrophages were then detached by trypsin treatment and subjected to flow cytometry analysis. CFSE positive THP-1 cells were regarded as cells having phagocyted at least one erythrocyte.

[0277] 1.8. Complement Activation Assay

[0278] For complement activation assays, RAJI cells were incubated with 5 g/ml of hCD20.sub.ScFv or hCD20.sub.ScFv-P18F3 in PBS 1% BSA for 1 h at 4 C. The cells were then washed twice with PBS 1% BSA and incubated for 1 h at 37 C., 5% CO.sub.2 with 10% EBV.sup.+ human plasma, in its active form of pre-inactivated by heat treatment (56 C. for 45 min). The cells were then washed three times with PBS and fixed with 4% PFA at room temperature for 15 min. The cells were then washed three times with PBS 5% BSA and blocked with PBS 5% BSA for 1 h at room temperature and then incubated with a mouse monoclonal antibody anti-C5b9 (Abcam ab66768, 1:100 in PBS 1% BSA). The cells were then washed three times with PBS 1% BSA and incubated for 30 min at room temperature with a PE-conjugated goat F(ab)2 anti-mouse IgG (Beckman Coulter, IM0855, diluted 1:100 in PBS 1% BSA). Cells were washed with PBS and subjected to flow cytometry analysis. Data was acquired using a BD FACScanto II flow cytometer (Becton-Dickinson, San Jose, Calif.) and analysis was performed using the FLOWJO 8.1 software (Tree Star Inc.). Cellular debris were excluded from the analysis by appropriated gating using the forward and side scatters. The C5-b9 deposition at the surface of RAJI cells was reflected by an increased fluorescence intensity in the PE channel.

1.9. Antibody-Dependent Cell Cytotoxicity (ADCC) Assay

[0279] For ADCC assays, RAJI cells were maintained at a density of 2.5.10.sup.5-10.sup.6 cells/ml in RPMI (Glutamax-I) supplemented with 10% FCS and 1 antibiotic-antimycotic solution (Gibco) at 37 C., 5% CO.sub.2. ADCC assays were performed using the ADCC Reporter Bioassay (Promega) according to manufacturer's instructions with slight modifications to fit our system. 300000 RAJI cells were first washed twice with PBS 2% BSA and incubated for 1 h at 4 C. with saturating concentration of conjugates (25 g/ml hCD20.sub.ScFv, hCD20.sub.ScFv-P18F3 or 50 g/ml VAR2CSA, VAR2CSA-P18F3. Cells were then washed once with PBS 2% BSA and 12500 cells (in 25 l) were introduced into the wells of white, flat bottom 96-well plates. EBV.sup.+ human plasma was inactivated/decomplemented at 56 C. for 45 min. Serial dilutions were prepared in ADCC assay medium (RPMI 1640, 4% low IgG FCS) and 25 l of diluted plasma were introduced to the wells together with the RAJI target cells. Effector cells were thawed and 75000 cells (in 25 l) were immediately distributed into the wells. Plates were incubated at 37 C., 5% CO.sub.2. After 6 h incubation, plates were removed from the incubator and let at room temperature for 15 min before addition of 75 l of Bio-Glo reagent into each well. Luminescence was measured using a VICTOR plate reader platform (PerkinElmer).

2. Results

[0280] 2.1. Expression and Purification of the Conjugates

[0281] The IMAC (Immobilized Metal ion Affinity Chromatography) purification in native conditions of the conjugates DARC.sub.VHH-EBV P18 and DARC.sub.VHH-EBV P23 (anti-DARC.sub.VHH fused to EBV P18 or EBV P23 antigen, respectively, each of said antigen being tagged in C-terminal with a poly-histidine sequence) was not successful (FIG. 1A-B). Indeed, the C-terminal His-tag was not accessible in native conditions as demonstrated by the successful purification of these conjugates by IMAC under denaturating conditions (FIG. 1C-D). Attempts to purify

[0282] N-terminal His-tagged fusions did not lead to better results.

[0283] A site-directed mutagenesis substituting the EBV P18 Cys (in amino-acid position 56) and the EBV P23 Cys (in amino-acid position 46) by serines was performed. The new conjugates DARC.sub.VHH-EBV P18 (C565)* and DARC-EBV P23 (C465)* were successfully purified by IMAC (FIG. 2). Nevertheless, the second step of the purification process (chromatography) revealed that a large proportion of the fusion proteins tended to form aggregates even in high-salt buffers (FIG. 3A and 4A).

[0284] To overcome this problem, shorter variants pf P18 and P23 were designed. The resulting fusion proteins DARC.sub.VHH-EBV P18F2, DARC.sub.VHH-EBV P18F3, DARC.sub.VHH-EBV P18F4 considerably gained in solubility compared to DARC.sub.VHH-EBV P18(C56S)* and formed very little aggregates during the gel filtration purification step (FIG. 3B-E). A similar approach was performed to improve DARC.sub.VHH-EBV P23 (C465)* solubility (data not shown).

[0285] In order to extend the proof of concept to another conjugation system, a VHH sequence capable to recognize a P. falciparum protein present at the surface of erythrocytes of placental origin infected by P. falciparum (VAR2CSA.sub.VHH) was also fused to the EBV P18 and EBV P23 antigens. Similarly to the DARC.sub.VHH conjugates, removal of N-terminal clusters of EBV P18 and EBV P23 drastically improved conjugate solubility and stability in solution. Gel electrophoresis analysis of all the produced constructs revealed the high purity of the recombinant proteins used in the study (FIG. 4B,).

[0286] The affinity of the DARC.sub.VHH-EBV P18 antigen conjugates and of the VAR2CSA.sub.VHH EBV P18 antigen conjugates for their respective molecular target was assessed by surface plasmon resonance. The specificity and affinity of the conjugates for their targets was not significantly modified in comparison to the affinity of the VHHs alone (FIG. 5).

[0287] The proof of concept of the invention was further validated with three other conjugation systems: [0288] a scFv sequence capable of recognizing CD20 (a marker typically overexpressed by cancer cells) fused to the EBV P18F3 antigen, of which the purification was successful (FIG. 10); and [0289] the EPCR receptor fused to the EBV P18F3 antigen, of which the purification was also successful (FIG. 16). [0290] The VAR2CSA variant protein fused to the EBV P18F3 antigen, of which the purification was also successful (FIG. 10)

[0291] 2.2. Immune Recognition of the Conjugates

[0292] Immunoglobulin G titers, reflecting the immune recognition of the conjugates, were determined by serial dilutions of plasma from 12 healthy donors positive for EBV infection. DARC.sub.VHH-EBV P18F2 was highly recognized by the IgG present in said plasma (Table 2 and FIG. 6A). Similar data were obtained with the conjugates DARC.sub.VHH-EBV P18 (C56S)*, and DARC.sub.VHH-EBV P23 (C46S)*.

TABLE-US-00016 TABLE 2 IgG titers (anti-DARCVHH-EBV P18F2) in plasma from 12 EBV+ donors. Donor ID IgG titers #20120621 460 #20120617 840 #20120312 230 #20120327 190 #20121029 130 #20120618 70 #20121001 440 #20120220 120 #20130313 360 #20120820 60 #20150217I 430 #20150217II 2300 Mean (SD): 470 (618)

[0293] A comparative immune recognition study performed with 22 plasma samples (dilution 1/200) showed that the C-terminal part of P18 possesses immuno-dominant epitopes. No significant differences in recognition was observed between conjugates comprises EBV P18F2 and EBV P18F3.

[0294] 2.3. Cell Surface Recognition of the Conjugates

[0295] Recognition of the native target by the conjugates was assessed by flow cytometry.

[0296] DARC.sub.VHH-EBV P18F2 was able to coat the surface of FY+ (DARC+) erythrocytes in a dose dependent manner (FIG. 7). Less than 250 ng of DARC.sub.VHH-EBV P18F2 was sufficient to saturate all the VHH-specific DARC-epitopes present on 1,000,000 red blood cells. In a similar manner, VAR2CSA.sub.VHH-EBV P18F2 was able to coat P. falciparum infected erythrocytes expressing VAR2CSA on their surface.

[0297] The hCD20.sub.ScFv-P18F3 conjugate was able to coat CD20.sup.+ RAJI cells (FIG. 11).

[0298] The VAR2CSA-P18F3 conjugate was able to coat CSA.sup.+ RAJI cells (FIG. 11).

[0299] The EPCR-P18F3 conjugate was able to coat the surface of VAR19-expressing erythrocytes, in a dose dependent manner (FIG. 17).

[0300] 2.4. Erythrocytes Opsonization by the Conjugates Targeting Said Cells

[0301] Furthermore, incubation of cell-bound conjugates with plasma samples of EBV+ donors led to FY+ (DARC+) erythrocytes opsonization, i.e. coating of cells with the donor plasma IgG (FIG. 8A). This was also illustrated in agglutination assays where successive incubation of FY+ erythrocytes with DARC.sub.VHH-EBV P18F3 and human plasma (EBV positive) led to cell agglutination (FIG. 8B).

[0302] 2.5. Opsonic Phagocytosis Assays

[0303] Phagocytic assays revealed an increased opsonic phagocytosis of erythrocytes by THP1 monocytes upon treatment with DARC.sub.VHH-EBV P18 and EBV P23 antigen fusions. Indeed, the conjugate DARC.sub.VHH-EBV P18 (C56S)* mediated an opsonic phagocytosis of FY+ red-blood cells by THP1-derived macrophages (FIG. 9A). Similar observations were made upon treatment with DARC.sub.VHH-EBV P18F3 (FIG. 9B), and also with the EPCR-P18F3 conjugate (using VAR19-expressing infected erythrocytes) (FIG. 18).

[0304] Incubation of cell-bound hCD20.sub.ScFv-P18F3 and VAR2CSA-P18F3 conjugates with plasma samples of EBV+ donors also led to RAJI opsonization, i.e. coating of cells with the donor plasma IgG (FIGS. 12 and 13).

[0305] Interestingly, treatment of FY+ red-blood cells with DARC.sub.VHH fused to different EBV P18 fragments revealed a link between the capability of said fragments to recruit IgG and the intensity of the elicited cellular response (FIG. 9C). Notably, the results of FIG. 9C show (i) a correlation between the cellular response (phagocytosis) and the antibody titers (anti-P18) from the plasmas used for opsonisation, and (ii) a plasma reactivity to P18 differing between the different P18 fragments, the P18F3 antigen displaying a better response.

[0306] These results are the first promising in vitro data demonstrating that immune clearance of a define target cell can be achieved following treatment with binding moeity-EBV P18 or EBV P23 fusion proteins.

[0307] 2.6. Complement Activation

[0308] Complement activation assays revealed an increased activation of the complement cascade upon treatment with the hCD20.sub.ScFv-P18F3 conjugate, most likely the classical antibody dependent pathway. This is illustrated by the formation of the membrane-attack complex at the cell surface that will result in target cell lysis (FIG. 14).

[0309] 2.7. ADCC

[0310] The ADCC assays revealed an increased activation of the NFAT pathway in competent effector cells by target cells (RAJI) pre-treated with either hCD20.sub.ScFv-P18F3 or VAR2CSA-P18F3. This reflects that opsonization of target cells occurring in presence of EBV+ plasma is leading to engagement of surface Fc receptors on effector cells and subsequent activation of intracellular pathways that will ultimately lead to target cell lysis (FIG. 15).

3. Conclusion

[0311] Immunotherapies are being used against cancer cells, infectious diseases as well as Alzheimer's disease. Interestingly, a recent study has shown that macrophages eliminate circulating tumor cells after monoclonal antibody therapy through dependent FcRI and FcRIV phagocytosis. No cell mediated Fc effector function are driven by antibody fragment or antibody-binding fragment or alternative proteic and non-proteic moieties including, without limitation, Fab antibodies, Fab antibodies, F(ab)2 antibodies, Fv antibodies, scFv antibodies, camelid single domain antibodies (VHH), and shark single domain antibodies (VNAR). One possibility is to fuse an Fc chain to those targeting moieties. However, adding an Fc chain will result in recombinant expression difficulties as well as decrease accessibility to epitopes present in small cavities and clefts.

[0312] The present invention proposes to overcome these issues with a new and innovative immunogenic construct, which is capable to redirect an EBV-existing (or pre-existing) immune response towards an undesired target cell and/or microorganism. In order to provide the proof of concept that a targeting moiety fused to an EBV antigen is capable to promote opsonization of a defined target, and the formation of immune complexes and subsequent clearance of said target, three in vitro models were used herein. In the first model, a single domain antibody (DARC.sub.VHH) targeting a protein expressed at the surface of erythrocytes was conjugated to a couple of different EBV antigens (either EBV P18 or EBV P23). In a second model, a single domain antibody (VAR2CSA.sub.VHH) and a proteic binding moiety not derived from antibodies (EPCR), both targeting malarial proteins expressed at the surface of Plasmodium falciparum infected erythrocytes (VAR2CSA.sup.PfEMP1 and VAR19.sup.PfEMP1, respectively) were conjugated to EBV P18. In a third model, an scFv antibody (hCD20.sub.ScFv) directed towards the Cluster of Differentiation CD20 and a proteic binding moiety not derived from antibodies (VAR2CSA), targeting respectively the CD20 molecules present at the surface of B cells (including B lymphomas) or the CSA over-expressed at the surface of cancer cells were conjugated to EBV P18.

[0313] The present study demonstrates the capacity of the designed conjugates to opsonize the target cells, respectively erythrocytes, Plasmodium falciparum infected erythrocytes, cancer cells and promote their clearance by immune effector mechanisms namely opsonic phagocytosis, ADCC and CDC.

[0314] The N-terminal regions of EBV P18 and EBV P23 were identified as an obstacle for protein expression, which considerably decreased protein solubility and stability. The deletion of N-terminal segments of EBV P18 and EBV P23 allowed soluble expression and purification of the conjugates (FIG. 1-4). The presence of a protein linker between the VHH and the EBV antigens was not mandatory for correct protein production.

[0315] Importantly, surface plasmon resonance experiments showed that the affinity and specificity of the binding moieties (DARC.sub.VHH and VAR2CSA.sub.VHH) for their defined targets was not affected by their fusion to an EBV-antigen (FIG. 5).

[0316] Immune recognition experiments performed with plasma from EBV positive individuals revealed that the conjugates comprising either EBV P18 or EBV P23 were highly recognized by circulating IgG (FIG. 6). Although F4 was still efficient to recruit IgG, the conjugates comprising the EBV P18 fragment EBV P18F3 (8.4 kDa) appeared to be the shortest fragment of EBV P18 giving maximum IgG reactivity. EBV P18F3 appeared as an adequate EBV antigen to be fused to diverse binding moieties and would allow the recruitment a variety of immune effectors to the target site. This was further confirmed by i) aggregation assays in which DARC.sub.VHH-EBV P18F3 was showed to mediate aggregation of erythrocytes in the presence of EBV+ human plasma (FIG. 8) and ii) by opsonization assays in which EPCR-EBV P18F3, hCD20.sub.ScFv-EBV P18F3 and VAR2CSA-EBV P18F3 were shown to recruit plasma IgG to the surface of infected erythrocytes (for EPCR-EBV P18F3) and to the surface of RAJI cancer cells (for hCD20.sub.ScFv-EBV P18F3 and VAR2CSA-EBV P18F3) thus leading to the formation of immune complexes (FIGS. 12, 13 and 17).

[0317] Of major interest, the formation of immune complexes mediated by the conjugates led to immune effector responses. DARC.sub.VHH-EBV P18F3 treatment of DARC+ erythrocytes promoted their elimination by macrophages (FIG. 9). In line with the results of EBV fragments immune recognition, DARC.sub.VHH-EBV P18F3 was more potent to induce opsonic phagocytosis than DARC.sub.VHH-EBV P18F4 (FIG. 9).

[0318] Furthermore, treatments of target cells with P18F3 conjugates also led to i) ADCC by competent effector cells (FIG. 15) and ii) activation of the complement cascade (FIG. 15) and formation of a MAC (membrane-attack complex) at the surface of the target cell.

[0319] Taken together, these results demonstrate that immunogenic constructs, such as DARC.sub.VHH-EBV P18F3, EPCR-EBV P18F3, hCD20.sub.ScFv-EBV P18F3 and VAR2CSA-EBV P18F3 are able to redirect an existing EBV immune response towards a specific target sequentially leading to the formation of immune complexes and subsequent recruitment of immune effector mechanisms such as opsonic phagocytosis, ADCC and CDC which ultimately lead to target elimination.

[0320] The types of agents, stable, easy to produce and highly efficient at opsonizing a target element are extremely valuable for clinical interventions either alone or in combination with existing therapies to fight pathogens and cancers.

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